ID

45985

Description

Principal Investigator: Nicholas O. Davidson, MD, Washington University, St. Louis, MO, USA MeSH: Familial Adenomatous Polyposis,Colonic Neoplasms https://www.ncbi.nlm.nih.gov/projects/gap/cgi-bin/study.cgi?study_id=phs000904 The ~80% of individuals with classic familial adenomatous polyposis (FAP) have detectable mutations in the coding sequence of the adenomatous polyposis coli (APC) gene. To investigate the 20% of families without detectable causative mutations, we used exome sequencing and second-generation sequencing of the APC locus including non-coding regions. We identified a novel ~11kb deletion 44kb upstream of APC that was present only in affected individuals of three kindreds. SNP analysis showed that this ~11kb deletion was accompanied by silencing of one of the APC alleles in blood-derived RNA of affected individuals.

Lien

dbGaP study=phs000904

Mots-clés

  1. 06/04/2024 06/04/2024 - Madita Rudolph
Détendeur de droits

Nicholas O. Davidson, MD, Washington University, St. Louis, MO, USA

Téléchargé le

6 avril 2024

DOI

Pour une demande vous connecter.

Licence

Creative Commons BY 4.0

Modèle Commentaires :

Ici, vous pouvez faire des commentaires sur le modèle. À partir des bulles de texte, vous pouvez laisser des commentaires spécifiques sur les groupes Item et les Item.

Groupe Item commentaires pour :

Item commentaires pour :

Vous devez être connecté pour pouvoir télécharger des formulaires. Veuillez vous connecter ou s’inscrire gratuitement.

dbGaP phs000904 APC Promoter Deletion in Classic Familial Adenomatous Polyposis

Eligibility Criteria

Inclusion and exclusion criteria
Description

Inclusion and exclusion criteria

Alias
UMLS CUI [1,1]
C1512693
UMLS CUI [1,2]
C0680251
*Inclusion Criteria:* Individuals with classic familial adenomatous polyposis were tested for known APC mutations with Colaris AP® (Myriad Genetic Laboratories). Those without detectable mutations by Colaris AP® and consenting family members were enrolled.
Description

Elig.phs000904.v1.p1.1

Type de données

boolean

Alias
UMLS CUI [1,1]
C1512693
UMLS CUI [1,2]
C0032580
UMLS CUI [1,3]
C4522286
UMLS CUI [1,4]
C0039593
UMLS CUI [2,1]
C1512693
UMLS CUI [2,2]
C0021430
UMLS CUI [2,3]
C0086282
*Exclusion Criteria:* Individuals with sporadic gastrointestinal cancer or a family history of cancer not suggestive of hereditary or familial diseases were excluded.
Description

Elig.phs000904.v1.p1.2

Type de données

boolean

Alias
UMLS CUI [1,1]
C0680251
UMLS CUI [1,2]
C0685938
UMLS CUI [1,3]
C0205422
UMLS CUI [2,1]
C0680251
UMLS CUI [2,2]
C0260515
UMLS CUI [2,3]
C0019247
UMLS CUI [2,4]
C1272460

Similar models

Eligibility Criteria

Name
Type
Description | Question | Decode (Coded Value)
Type de données
Alias
Item Group
Inclusion and exclusion criteria
C1512693 (UMLS CUI [1,1])
C0680251 (UMLS CUI [1,2])
Elig.phs000904.v1.p1.1
Item
*Inclusion Criteria:* Individuals with classic familial adenomatous polyposis were tested for known APC mutations with Colaris AP® (Myriad Genetic Laboratories). Those without detectable mutations by Colaris AP® and consenting family members were enrolled.
boolean
C1512693 (UMLS CUI [1,1])
C0032580 (UMLS CUI [1,2])
C4522286 (UMLS CUI [1,3])
C0039593 (UMLS CUI [1,4])
C1512693 (UMLS CUI [2,1])
C0021430 (UMLS CUI [2,2])
C0086282 (UMLS CUI [2,3])
Elig.phs000904.v1.p1.2
Item
*Exclusion Criteria:* Individuals with sporadic gastrointestinal cancer or a family history of cancer not suggestive of hereditary or familial diseases were excluded.
boolean
C0680251 (UMLS CUI [1,1])
C0685938 (UMLS CUI [1,2])
C0205422 (UMLS CUI [1,3])
C0680251 (UMLS CUI [2,1])
C0260515 (UMLS CUI [2,2])
C0019247 (UMLS CUI [2,3])
C1272460 (UMLS CUI [2,4])

Utilisez ce formulaire pour les retours, les questions et les améliorations suggérées.

Les champs marqués d’un * sont obligatoires.

Do you need help on how to use the search function? Please watch the corresponding tutorial video for more details and learn how to use the search function most efficiently.

Watch Tutorial