ID

45985

Description

Principal Investigator: Nicholas O. Davidson, MD, Washington University, St. Louis, MO, USA MeSH: Familial Adenomatous Polyposis,Colonic Neoplasms https://www.ncbi.nlm.nih.gov/projects/gap/cgi-bin/study.cgi?study_id=phs000904 The ~80% of individuals with classic familial adenomatous polyposis (FAP) have detectable mutations in the coding sequence of the adenomatous polyposis coli (APC) gene. To investigate the 20% of families without detectable causative mutations, we used exome sequencing and second-generation sequencing of the APC locus including non-coding regions. We identified a novel ~11kb deletion 44kb upstream of APC that was present only in affected individuals of three kindreds. SNP analysis showed that this ~11kb deletion was accompanied by silencing of one of the APC alleles in blood-derived RNA of affected individuals.

Link

dbGaP study=phs000904

Keywords

  1. 4/6/24 4/6/24 - Madita Rudolph
Copyright Holder

Nicholas O. Davidson, MD, Washington University, St. Louis, MO, USA

Uploaded on

April 6, 2024

DOI

To request one please log in.

License

Creative Commons BY 4.0

Model comments :

You can comment on the data model here. Via the speech bubbles at the itemgroups and items you can add comments to those specificially.

Itemgroup comments for :

Item comments for :

In order to download data models you must be logged in. Please log in or register for free.

dbGaP phs000904 APC Promoter Deletion in Classic Familial Adenomatous Polyposis

Eligibility Criteria

Inclusion and exclusion criteria
Description

Inclusion and exclusion criteria

Alias
UMLS CUI [1,1]
C1512693
UMLS CUI [1,2]
C0680251
*Inclusion Criteria:* Individuals with classic familial adenomatous polyposis were tested for known APC mutations with Colaris AP® (Myriad Genetic Laboratories). Those without detectable mutations by Colaris AP® and consenting family members were enrolled.
Description

Elig.phs000904.v1.p1.1

Data type

boolean

Alias
UMLS CUI [1,1]
C1512693
UMLS CUI [1,2]
C0032580
UMLS CUI [1,3]
C4522286
UMLS CUI [1,4]
C0039593
UMLS CUI [2,1]
C1512693
UMLS CUI [2,2]
C0021430
UMLS CUI [2,3]
C0086282
*Exclusion Criteria:* Individuals with sporadic gastrointestinal cancer or a family history of cancer not suggestive of hereditary or familial diseases were excluded.
Description

Elig.phs000904.v1.p1.2

Data type

boolean

Alias
UMLS CUI [1,1]
C0680251
UMLS CUI [1,2]
C0685938
UMLS CUI [1,3]
C0205422
UMLS CUI [2,1]
C0680251
UMLS CUI [2,2]
C0260515
UMLS CUI [2,3]
C0019247
UMLS CUI [2,4]
C1272460

Similar models

Eligibility Criteria

Name
Type
Description | Question | Decode (Coded Value)
Data type
Alias
Item Group
Inclusion and exclusion criteria
C1512693 (UMLS CUI [1,1])
C0680251 (UMLS CUI [1,2])
Elig.phs000904.v1.p1.1
Item
*Inclusion Criteria:* Individuals with classic familial adenomatous polyposis were tested for known APC mutations with Colaris AP® (Myriad Genetic Laboratories). Those without detectable mutations by Colaris AP® and consenting family members were enrolled.
boolean
C1512693 (UMLS CUI [1,1])
C0032580 (UMLS CUI [1,2])
C4522286 (UMLS CUI [1,3])
C0039593 (UMLS CUI [1,4])
C1512693 (UMLS CUI [2,1])
C0021430 (UMLS CUI [2,2])
C0086282 (UMLS CUI [2,3])
Elig.phs000904.v1.p1.2
Item
*Exclusion Criteria:* Individuals with sporadic gastrointestinal cancer or a family history of cancer not suggestive of hereditary or familial diseases were excluded.
boolean
C0680251 (UMLS CUI [1,1])
C0685938 (UMLS CUI [1,2])
C0205422 (UMLS CUI [1,3])
C0680251 (UMLS CUI [2,1])
C0260515 (UMLS CUI [2,2])
C0019247 (UMLS CUI [2,3])
C1272460 (UMLS CUI [2,4])

Please use this form for feedback, questions and suggestions for improvements.

Fields marked with * are required.

Do you need help on how to use the search function? Please watch the corresponding tutorial video for more details and learn how to use the search function most efficiently.

Watch Tutorial