ID

45409

Beschreibung

Principal Investigator: Luigi D. Notarangelo, MD, Division of Immunology, Boston Children's Hospital; Harvard Stem Cell Institute, Harvard Medical School, Boston, MA, USA MeSH: https://www.ncbi.nlm.nih.gov/projects/gap/cgi-bin/study.cgi?study_id=phs000641 Combined Immunodeficiency with Multiple Intestinal Atresias (CID-MIA) is a rare genetic disorder with the cause previously unknown. Symptoms of CID-MIA include atresias in the small and/or large intestine, as well as immunodeficiency. In this study, we sequenced the whole exome of 5 unrelated CID-MIA patients as well as their healthy family members, and identified deleterious homozygous or compound heterozygous mutations in the gene *TTC7A* in all the 5 patients, as well as in 3 additional patients with Sanger sequencing. Our findings strongly indicate *TTC7A* dysfunction to be the cause for CID-MIA.

Link

dbGaP study = phs000641

Stichworte

  1. 19.11.22 19.11.22 - Simon Heim
Rechteinhaber

Luigi D. Notarangelo, MD, Division of Immunology, Boston Children's Hospital; Harvard Stem Cell Institute, Harvard Medical School, Boston, MA, USA

Hochgeladen am

19. November 2022

DOI

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Lizenz

Creative Commons BY 4.0

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dbGaP phs000641 TTC7A Mutations for Combined Immunodeficiency with Intestinal Atresia

Eligibility Criteria

Inclusion and exclusion criteria
Beschreibung

Inclusion and exclusion criteria

Alias
UMLS CUI [1,1]
C1512693
UMLS CUI [1,2]
C0680251
*Inclusion Criteria:*
Beschreibung

*Inclusion Criteria:*

Datentyp

boolean

Alias
UMLS CUI [1,1]
C1512693
Families with probands with Combined Immunodeficiency with Multiple Intestinal Atresias (CID-MIA).
Beschreibung

Families with probands with Combined Immunodeficiency with Multiple Intestinal Atresias (CID-MIA).

Datentyp

boolean

Alias
UMLS CUI [1,1]
C0015576
UMLS CUI [1,2]
C0702111
UMLS CUI [1,3]
C2711630
UMLS CUI [1,4]
C0220744
*Exclusion Criteria:* N. A.
Beschreibung

*Exclusion Criteria:* N. A.

Datentyp

boolean

Alias
UMLS CUI [1,1]
C0680251

Ähnliche Modelle

Eligibility Criteria

Name
Typ
Description | Question | Decode (Coded Value)
Datentyp
Alias
Item Group
Inclusion and exclusion criteria
C1512693 (UMLS CUI [1,1])
C0680251 (UMLS CUI [1,2])
*Inclusion Criteria:*
Item
*Inclusion Criteria:*
boolean
C1512693 (UMLS CUI [1,1])
Families with probands with Combined Immunodeficiency with Multiple Intestinal Atresias (CID-MIA).
Item
Families with probands with Combined Immunodeficiency with Multiple Intestinal Atresias (CID-MIA).
boolean
C0015576 (UMLS CUI [1,1])
C0702111 (UMLS CUI [1,2])
C2711630 (UMLS CUI [1,3])
C0220744 (UMLS CUI [1,4])
*Exclusion Criteria:* N. A.
Item
*Exclusion Criteria:* N. A.
boolean
C0680251 (UMLS CUI [1,1])

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